Corkscrew angiopathy of intracranial vessels in a young stroke patient: a case report

Journal of Medical Case Reports

Sagar P Oak¹  Lakshmi Sudha P Karanam¹  Anand Alurkar¹ 

[1] Department of Neurointervention, KEM Hospital, Pune, India

关键词: Digital subtraction angiography;    Stroke;    Corkscrew angiopathy;   

Others  :  1195330
DOI  :  10.1186/1752-1947-6-358

 received in 2012-04-04, accepted in 2012-08-11,  发布年份 2012

【 摘 要 】

Introduction

We present a rare finding of a ‘corkscrew appearance’ of the distal cerebral vessels in a young Asian woman who presented with acute stroke.

Case presentation

A 32-year-old Asian woman presented with a 3-month history of recurrent right-sided transient ischemic attacks. Her clinical workup and brain imaging results were normal. A digital subtraction angiogram revealed an abnormal corkscrew appearance of all intracranial distal vessels. She was discharged on a single antiplatelet drug. She had no further transient ischemic attacks on clinical follow-up. A digital subtraction angiogram performed 1 year later revealed no changes in the appearance of these vessels.

Conclusion

To the best of our knowledge no similar previous reports exist in the literature. The present report describes a unique case of an unusual corkscrew appearance of the distal intracranial vessels. However, the underlying etiology in the present case remains unknown.

【 授权许可】

   
2012 Alurkar et al.; licensee BioMed Central Ltd.

【 图 表 】

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