Dieulafoy’s disease of the bronchus: report of a case and review of the literature

Journal of Cardiothoracic Surgery

Bin Wang¹  Qingchen Wu¹  Yu Fang¹ 

[1] Department of Thoracic & Cardiovascular Surgery, The First Affiliated Hospital of Chongqing Medical University, 1 Youyi Road, Chongqing, 400016, Yuzhong District, China

关键词: Bronchial artery;    Lobectomy;    Embolization;    Hemoptysis;    Dieulafoy’s disease of bronchus;   

Others  :  1136123
DOI  :  10.1186/s13019-014-0191-8

 received in 2014-08-31, accepted in 2014-11-20,  发布年份 2014

【 摘 要 】

Background

Dieulafoy’s disease is a vascular anomaly characterized by the presence of a tortuous dysplastic artery in the submucosa. Although frequently occurring in the gastrointestinal tract, multiple cases of Dieulafoy’s disease in the bronchus have been reported in the literature.

Methods and results

We report a case of a 15-year-old boy suffering recurrent massive hemoptysis. Bilobectomy stopped bleeding after unsuccessful treatment with embolization of bronchial artery.

Conclusion

It is concluded a congenital origin of this disease. Angiography and endobronchial ultrasonography can be used to diagnose Dieulafoy’s disease of bronchus whereas bronchoscopy biopsy should be avoided. Surgery is needed when embolization fails.

【 授权许可】

   
2014 Fang et al.; licensee BioMed Central Ltd.

【 图 表 】

Figure 1.

Figure 2.

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