Very late recurrence of sinus of Valsalva aneurysm rupture after patch repair

BMC Surgery

Chih-Chen Wu¹  Cheng-Pin Lee¹  Tsung-Yan Chen²  Lin Lin¹  Hsiao-En Tsai²  Ting-Tse Lin¹ 

[1] Division of Cardiology, Department of Internal Medicine, National Taiwan University College of Medicine and Hospital Hsin-Chu Branch, No.25, Ln. 442, Sec. 1, Jingguo Rd., North Dist., Hsinchu City 300, Taiwan;Department of Surgery, National Taiwan University College of Medicine and Hospital Hsin-Chu Branch, Hsin-Chu City, Taiwan

关键词: Left-to-right shunt;    Patch repair;    Ruptured Sinus of Valsalva aneurysm;   

Others  :  1091861
DOI  :  10.1186/1471-2482-14-73

 received in 2014-05-31, accepted in 2014-09-23,  发布年份 2014

【 摘 要 】

Background

Sinus of Valsalva aneurysm (SVA) is an uncommon cardiac defect accounting for only 1% of congenital cardiac anomalies and the most common complication is ruptured into the atrium or ventricle. Very late recurrence of ruptured SVA after patch repair is extremely rare.

Case presentation

We present a case of 57-year-old man had received repair for ruptured Sinus of Valsalva aneurysm at 19 ages. In the clinics, he presented with exertional dyspnea and leg swelling. The serial examination disclosed he had bicuspid aortic valve and very late rupture of SVA connecting to right atrium. After surgical repair again, he was discharged smoothly.

Conclusion

A very late recurrence of ruptured SVA after surgical repair was rare. We reported a case with unique echocardiographic presentation and a successful repair.

【 授权许可】

   
2014 Lin et al.; licensee BioMed Central Ltd.

【 图 表 】

Figure 1.

Figure 2.

Figure 3.

Figure 4.

【 参考文献 】

• [1]Wang KY, St John Sutton M, Ho HY, Ting CT: Congenital sinus of Valsalva aneurysm: a multiplane transesophageal echocardiographic experience. J Am Soc Echocardiogr 1997, 10:956-963.
• [2]Meier JH, Seward JB, Miller FA Jr, Oh JK, Enriquez-Sarano M: Aneurysms in the left ventricular outflow tract: clinical presentation, causes, and echocardiographic features. J Am Soc Echocardiogr 1998, 11:729-745.
• [3]Chu SH, Hung CR, How SS, Chang H, Wang SS, Tsai CH, Liau CS, Tseng CD, Tseng YZ, Lee YT, Lien WP, Lue HC, Lin TY: Ruptured aneurysms of the sinus of Valsalva in Oriental patients. J Thorac Cardiovasc Surg 1990, 99:288-298.
• [4]van Son JA, Danielson GK, Schaff HV, Orszulak TA, Edwards WD, Seward JB: Long-term outcome of surgical repair of ruptured sinus of Valsalva aneurysm. Circulation 1994, 90:II20-II29.
• [5]Moustafa S, Mookadam F, Cooper L, Adam G, Zehr K, Stulak J, Holmes D: Sinus of Valsalva aneurysms–47 years of a single center experience and systematic overview of published reports. Am J Cardiol 2007, 99:1159-1164.