期刊论文详细信息
BMC Health Services Research
Wheelchair interventions, services and provision for disabled children: a mixed-method systematic review and conceptual framework
Nigel Harris1  Rhiannon T Edwards2  Jane Noyes3  Nathan Bray3 
[1] DesignAbility, Bath Institute of Medical Engineering, The Wolfson Centre, Royal United Hospital, Bath BA1 3NG, UK;Centre for Health Economics and Medicines Evaluation, Bangor University, Ardudwy Building, Normal Site, Bangor University, Bangor, Gwynedd LL57 2PZ, UK;Centre for Health-Related Research, Fron Heulog, Bangor University, Bangor, Gwynedd LL57 2EF, UK
关键词: Health economics;    Conceptual framework;    Systematic review;    Powered wheelchair;    Children;    Assistive mobility technology;    Childhood disability;    Wheelchair;   
Others  :  865474
DOI  :  10.1186/1472-6963-14-309
 received in 2013-02-06, accepted in 2014-07-11,  发布年份 2014
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【 摘 要 】

Background

Wheelchairs for disabled children (≤18 years) can provide health, developmental and social benefits. World Health Organisation and United Kingdom Government reports demonstrate the need for improved access to wheelchairs both locally and internationally. The use of health economics within this field is lacking. Provision of wheelchairs based on cost-effectiveness evidence is not currently possible. We conducted the first systematic review in this field to incorporate evidence of effectiveness, service user perspectives, policy intentions and cost-effectiveness in order to develop a conceptual framework to inform future research and service development.

Methods

We used an adapted EPPI-Centre mixed-method systematic review design with narrative summary, thematic and narrative synthesis. 11 databases were searched. Studies were appraised for quality using one of seven appropriate tools. A conceptual framework was developed from synthesised evidence.

Results

22 studies and 14 policies/guidelines were included. Powered wheelchairs appear to offer benefits in reduced need for caregiver assistance; improved communicative, personal-social and cognitive development; and improved mobility function and independent movement. From 14 months of age children can learn some degree of powered wheelchair driving competence. However, effectiveness evidence was limited and low quality. Children and parents placed emphasis on improving social skill and independence. Participation in wider society and development of meaningful relationships were key desired outcomes. Policy intentions and aspirations are in line with the perspectives of children and parents, although translation of policy recommendations into practice is lacking.

Conclusions

There is a distinct lack of high quality effectiveness and economic evidence in this field. Social and health needs should be seen as equally important when assessing the mobility needs of disabled children. Disabled children and parents placed highest priority on independence and psychosocial outcomes of wheelchair interventions. Translation of policy and guidelines into practice is lacking and more effective implementation strategies are required to improve services and outcomes. Future research should focus on outcome measure development, developing economic evaluation tools and incorporating these into high quality studies to address known research gaps. The novel conceptual framework maps current gaps in evidence and outlines areas for development.

【 授权许可】

   
2014 Bray et al.; licensee BioMed Central Ltd.

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【 参考文献 】
  • [1]World Health Organisation: Concept Note. World Report on Disability and Rehabilitation. Geneva, World Health Organization. Geneva: World Health Organization; 2008. [http://www.who.int/disabilities/publications/dar_world_report_concept_note.pdf]
  • [2]World Health Organization: World Report on Disability. Geneva: World Health Organization; 2011. [http://whqlibdoc.who.int/publications/2011/9789240685215_eng.pdf]
  • [3]Sheldon S, Jacobs NA (Eds): Report of a Consensus Conference on Wheelchairs for Developing Countries, Bangalore, India, 6–11 November 2006. Copenhagen: International Society for Prosthetics and Orthotics; 2007. [http://pdf.usaid.gov/pdf_docs/PNADP827.pdf]
  • [4]World Health Organization: Guidelines on the Provision of Manual Wheelchairs in Less-Resourced Settings. Geneva: World Health Organization; 2008. [http://www.who.int/disabilities/publications/technology/wheelchairguidelines/en/index.html]
  • [5]United Nations: The Standard Rules on the Equalization of Opportunities for Persons with Disabilities. Preconditions for Equal Participation. 1993. [http://www.un.org/esa/socdev/enable/dissre03.htm]
  • [6]World Health Organization: The Global Burden of Disease: 2004 Update. Geneva: World Health Organization; 2008. [http://www.who.int/healthinfo/global_burden_disease/GBD_report_2004update_full.pdf]
  • [7]Lau H, Tam EWC, Cheng JCY: An experience on wheelchair bank management. Disabil Rehabil Assist Technol 2008, 3(6):302-308.
  • [8]Welsh Assembly Government: National Service Framework for Children, Young People and Maternity Services in Wales. Cardiff: Welsh Assembly Government; 2005.
  • [9]Department of Health Commissioning Team: Local Innovation in Wheelchair and Seating Services. London: Department of Health; 2010.
  • [10]Contact a Family: Annual Review: How we Made a Difference in 2010/2011. London: Contact a Family; 2011. [http://www.cafamily.org.uk/media/447274/contact_a_family_annual_review_2010-11a.pdf]
  • [11]National Assembly for Wales Health, Wellbeing and Local Government Committee: Report on Inquiry into Wheelchair Services in Wales. Cardiff: National Assembly for Wales; 2010.
  • [12]Audit Commission: Fully Equipped 2002- Assisting Independence. Wetherby: Audit Commission Publications; 2002.
  • [13]NHS Modernisation Agency: Improving Services for Wheelchair Users and Carers- Good Practice Guide. London: Department of Health; 2005.
  • [14]Prime Minister’s Strategy Unit Report: ‘Improving the Life Chances of Disabled People.’ Joint Report With Department for Work and Pensions, Health, Education and Skills and the Office of the Deputy Prime Minister. London: Department for Work and Pensions, Health, Education and Skills; 2005. [http://webarchive.nationalarchives.gov.uk/+/http:/www.cabinetoffice.gov.uk/media/cabinetoffice/strategy/assets/disability.pdf]
  • [15]Department of Health: Standard 8 of the Children’s National Service Framework: Disabled Children and Those With Complex Healthcare Needs. London: Department of Health; 2004.
  • [16]Oliver M: Theories of disability in health practice and research. BMJ 1998, 317:1446-1449.
  • [17]Centre for Reviews and Dissemination: Systematic Reviews: CRD’s Guidance for Undertaking Reviews in Health Care. York: University of York; 2009.
  • [18]Thomas J, Harden A: Methods for the thematic synthesis of qualitative research in systematic reviews. BMC Med Res Methodol 2008, 8:45.
  • [19]Oliver S, Harden A, Rees R: An emerging framework for including different types of evidence in systematic reviews for public policy. Evaluation 2005, 11(4):428-446.
  • [20]EPPI-Centre: EPPI-centre methods for conducting systematic reviews. 2010. [http://eppi.ioe.ac.uk/cms/LinkClick.aspx?fileticket=hQBu8y4uVwI%3d&tabid=88&mid=6162]
  • [21]Jones MA, McEwen IR, Hansen L: Use of power mobility for a young child with spinal muscular atrophy. Phys Ther 2003, 83(3):253-262.
  • [22]Furumasu J, Tefft D, Guerette P: The Impact of Early Powered Mobility on Young children’s Play and Psychosocial Skills. Proceedings of 24th International Seating Symposium, March 6–8, 2008; Vancouver 2008, 160-165.
  • [23]Jones MA, McEwan IR, Neas BR: Effects of Power Wheelchairs on the development and function of young children with severe motor impairment. Pediatr Phys Ther 2012, 24(2):131-140.
  • [24]Tefft D, Guerette P, Furumasu J: The impact of early powered mobility on parental stress, negative emotions, and family social interactions. Phys Occup Ther Pediatr 2011, 31(1):4-15.
  • [25]Bottos M, Bolcati C, Sciuto L, Ruggeri C, Feliciangeli A: Powered wheelchairs and independence in young children with tetraplegia. Dev Med Child Neurol 2001, 43(11):769-777.
  • [26]Deitz J, Swinth Y, White O: Powered mobility and preschoolers with complex developmental delays. Am J Occup Ther 2002, 56(1):86-96.
  • [27]Huhn K, Guarrera-Bowlby P, Deutsch JE: The clinical decision-making process of prescribing power mobility for a child with cerebral palsy. Pediatr Phys Ther 2007, 19(3):254-260.
  • [28]Meiser MJ, McEwen IR: Lightweight and ultralight wheelchairs: propulsion and preferences of two young children with spina bifida. Pediatr Phys Ther 2007, 19(3):245-253.
  • [29]Østensjø S, Carlberg EB, Vøllestad NK: The use and impact of assistive devices and other environmental modifications on everyday activities and care in young children with cerebral palsy. Disabil Rehabil 2005, 27(14):849-861.
  • [30]Benedict RE, Lee JP, Marrujo SK, Farel AM: Assistive devices as an early childhood intervention: evaluating outcomes. Technol Disabil 1999, 11(1):79-90.
  • [31]Wiart L, Darrah J, Hollis V, Cook A, May L: Mothers’ perceptions of their children’s use of powered mobility. Phys Occup Ther Pediatr 2004, 24(4):3-21.
  • [32]Durkin J: Discovering powered mobility skills with children: ‘responsive partners’ in learning. Int J Ther Rehabil 2009, 16(6):331-341.
  • [33]Guerette P, Tefft D, Furumasu J: Pediatric powered wheelchairs: results of a national survey of providers. Assist Technol 2005, 17(2):144-158.
  • [34]Home AM, Ham R: Provision of powered mobility equipment to young children: the Whizz-Kidz experience. Int J Ther Rehabil 2003, 10(11):511-519.
  • [35]Staincliffe S: Wheelchair services and providers: discriminating against disabled children? Int J Ther Rehabil 2003, 10(4):151-158.
  • [36]Wiart L, Darrah J, Cook A, Hollis V, May L: Evaluation of powered mobility use in home and community environments. Phys Occup Ther Pediatr 2003, 23(2):59-75.
  • [37]Evans S, Neophytou C, De Souza L, Frank AO: Young people’s experiences using electric powered indoor-outdoor wheelchairs (EPIOCs): Potential for enhancing users’ development? Disabil Rehabil 2007, 29(16):1281-1294.
  • [38]Lawlor K, Mihaylov S, Welsh B, Jarvis S, Colver A: A qualitative study of the physical, social and attitudinal environments influencing the participation of children with cerebral palsy in northeast England. Pediatr Rehabil 2006, 9(3):219-228.
  • [39]Shahid M: Buggy-to-wheelchair progression for children with cerebral palsy: parents’ and therapists’ opinions. Int J Ther Rehabil 2004, 11(12):560-566.
  • [40]Curtin M, Clarke G: Listening to young people with physical disabilities’ experiences of education. Int J Disabil Dev Educ 2005, 52(3):195-214.
  • [41]Muscular Dystrophy Campaign: Building on Foundations: Get Moving – the Case for Effective Wheelchair Services. London: Muscular Dystrophy Campaign; 2010.
  • [42]Muscular Dystrophy Campaign: Wheelchair Provision for Children and Adults With Muscular Dystrophy and Other Neuromuscular Conditions. London: Muscular Dystrophy Campaign; 2011.
  • [43]Barnardos and Whizz-Kidz: Don’t Push us Around. London: Whizz-Kidz; 2006.
  • [44]Care Services Improvement Partnership: Out and About- Wheelchairs as Part of a Whole-Systems Approach to Independence. London: Department of Health; 2006.
  • [45]HM Treasury and Department for Education and Skills: Aiming High for Disabled Children: Better Support for Families. London/Runcorn: HM Treasury/Department for Education and Skills; 2007.
  • [46]Scottish Executive: Moving Forward: Review of NHS Seating Services in Scotland. Edinburgh: Scottish Executive; 2006.
  • [47]All Party Parliamentary Group for Paediatric Reform and Whizz-Kidz: “My Wheelchair is my Shoes” Making the Case for Wheelchair Reform. London: Whizz-Kidz; 2011.
  • [48]Neilson A, Hogg J, Malek M, Rowley D: Impact of surgical and orthotic intervention on the quality of life of people with profound intellectual and multiple disabilities and their carers. J Appl Res Intellect Disabil 2000, 13:216-238.
  • [49]Curtis L, Netten A: Unit Costs of Health and Social Care 2006. Cantebury: Personal Social Services Research Unit, University of Kent; 2006. [http://www.pssru.ac.uk/archive/pdf/uc/uc2006/uc2006.pdf (last accessed 24/07/2012]
  • [50]Curtis L: Unit Costs of Health and Social Care 2011. Cantebury: Personal Social Services Research Unit, University of Kent; 2011. [http://www.pssru.ac.uk/pdf/uc/uc2011/uc2011.pdf]
  • [51]Frontier Economics: Impact of Whizz-Kidz Support to Primary Care Trusts. London: Frontier Economic Ltd; 2011.
  • [52]Professor the Lord Darzi of Denham KBE: High Quality Care for all: NHS Next Stage Review Final Report. London: Department of Health; 2008.
  • [53]Graham ID, Tetroe JM: Getting evidence into policy and practice: perspective of a health research funder. J Can Acad Child Adolesc Psychiatry 2009, 18(1):46-50.
  • [54]Stetler CB, Damschroder LJ, Helfrich CD, Hagedorn HJ: A Guide for applying a revised version of the PARIHS framework for implementation. Implement Sci 2011, 6:99.
  • [55]NHS Institute for innovation and Improvement: Spread and adoption tool. 2012. [http://www.institute.nhs.uk/index.php?option=com_spread_and_adoption]
  • [56]Posture and Mobility Group: The Future of Wheelchair Services - Any Qualified Provider?. Exeter: Posture and Mobility Group and British Healthcare Trades Association; 2011. [http://www.pmguk.co.uk/official-publications-and-reports.html]
  • [57]Demers L, Weiss-Lambrou R, Ska B: The Quebec User Evaluation of Satisfaction with Assistive Technology (QUEST 2.0): An overview and recent progress. Technol Disabil 2002, 14:101-105. [https://enablemob.wustl.edu/OT572D-01/RequiredArticles/QUEST%20article.pdf]
  • [58]Nord E, Daniels N, Kamlet M: QALYs: some challenges. Value Health 2009, 12:1 S10-S15. [http://www.ispor.org/meetings/invitational/QALY/Paper3.pdf]
  • [59]Horsman J, Furlong W, Feeny D, Torrance G: The Health Utilities Index (HUI): concepts, measurement properties and applications. Health Qual Life Outcomes 2003., 1(54) [http://www.hqlo.com/content/1/1/54]
  • [60]Varni JW, Burwinkle TM, Seid M: The PedsQL as a pediatric patient-reported outcome. Reliability and validity of the PedsQL measurement model in 25,000 children. Expert Rev Pharmacoecon Outcomes Res 2005, 5(6):705-719.
  • [61]National Institute for Health and Clinical Excellence: The guidelines manual. [http://publications.nice.org.uk/the-guidelines-manual-pmg6]
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